Diagram showing how a mutation in Luka's ATP6AP2 gene changes the amino acid from isoleucine to methionine, resulting in a nonfunctional protein. The top part shows correct gene transcription and translation producing a functional protein, while the bottom part shows a point mutation changing an adenine to guanine, leading to a different amino acid and a defective protein, marked with a red cross.

So what have we learn?!

After Luka became stable from the acute liver failure, he did every test under the sun to try and understand what caused the liver to fail. The doctors were at a loss. We would have been in a diagnostic desert without Gene sequencing. So what did we learn?

Diagram of a plant cell showing various organelles labeled with letters, including the nucleus, mitochondria, endoplasmic reticulum, Golgi apparatus, and other structures.

What’s happening in the body?

This disease is caused by a change (mutation) in a gene that helps control an important system inside our cells called a proton pump.

Proton pumps act like tiny regulators that control acidity (pH) inside different parts of the cell. That acidity is critical — it allows cells to make proteins, move them to the right place, and clean up waste.

When the proton pump doesn’t work properly, many systems inside the cell are affected.

PROTON PUMP

Illustration of the biochemical pathway converting glucose to CMP-sialic acid, showing steps involving UDP-GlcNAc, ManNAc, various phosphorylation and activation steps, and leading to the production of sialic acid and CMP-sialic acid.

What is the proton pump?

The affected protein is part of something called a V-ATPase (vacuolar ATPase).

Think of the V-ATPase as a battery-powered pump that moves protons to create the right level of acidity inside cell compartments.

These compartments include:

  • the Golgi apparatus (where proteins are modified and packaged)

  • the lysosome (the cell’s recycling and waste center)

  • the endoplasmic reticulum (where proteins are made)

Each of these areas needs a very specific acidity level to work properly.

Why does acidity (pH) matter?

The right acidity inside cells is essential for:

  • making proteins correctly

  • modifying sugars on proteins (glycosylation)

  • moving proteins to where they need to go

  • breaking down waste

  • supporting metabolism, muscle function, and brain development

When acidity is off, proteins may be made incorrectly, misplaced, or not broken down at all..

What goes wrong in this disease?

Illustration of the lifecycle of a virus, showing several stages from replication to infection of host cells, with cartoonish green and pink virus particles.

Because the proton pump doesn’t function well:

  • cell compartments don’t reach the acidity they need

  • proteins aren’t processed or cleared correctly

  • waste builds up inside cells instead of being recycled

One major system affected is autophagy.

What is autophagy?

Autophagy is the body’s clean-up and recycling system.

You can think of it like this:

  • the cell gathers broken or poorly made parts into a “trash bag” (called an autophagosome)

  • that trash bag is delivered to the lysosome

  • the lysosome breaks it down into reusable pieces

This process only works if the lysosome is acidic enough.

When lysosomes aren’t acidic:

  • waste doesn’t break down properly

  • junk builds up inside cells

  • cells become damaged over time

How does this affect the body?

Over time, the buildup of under-cleared waste can lead to:

  • liver disease, including cirrhosis

  • developmental and neurological challenges

  • problems affecting multiple organs

Similar problems with waste buildup and lysosomal function have also been linked to age-related conditions such as Parkinson’s, Alzheimer’s, and other neurodegenerative diseases.

Why this matters

Healthy cells depend on:

  • proper protein production (glycosylation in the Golgi)

  • effective waste removal (autophagy in the lysosome)

  • precise control of acidity

Mutations affecting the V-ATPase disrupt all of these systems at once — which is why this disease can affect many parts of the body.

Understanding these pathways helps guide research toward therapies that support both protein processing and cellular cleanup.

A close-up of scattered white pills on a surface.

OUR AIM:

To create a novel therapeutic that will address both glycosylation and autophagy issues.